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Title: | Performance of Upper Limb module for Duchenne muscular dystrophy | Authors: | Mayhew, Anna G. Coratti, Giorgia Mazzone, Elena Stacy KLINGELS, Katrijn James, Meredith Pane, Marika Straub, Volker Goemans, Natalie Mercuri, Eugenio Ricotti, Valeria Muntoni, Francesco Ridout, Deborah Selby, Victoria |
Issue Date: | 2019 | Publisher: | WILEY | Source: | DEVELOPMENTAL MEDICINE AND CHILD NEUROLOGY, 62(5), pp. 633-639 | Abstract: | AIM To report the differences between Performance of Upper Limb (PUL) versions 1.2 and 2.0, compare the measurement ability of the two versions, and compare their longitudinal performance in Duchenne muscular dystrophy. METHOD Rasch analysis was performed on the dual data from three centres to confirm whether the two scales measure the same construct. Change scores in natural history for the different domains were compared for the two versions. RESULTS Rasch analysis demonstrated that both versions measure the same construct and that the PUL 2.0 was a better fit to the construct of motor performance and better able to detect change at 12 months in all levels of ability than the PUL 1.2. This was also true when change scores were reviewed over 2 years. INTERPRETATION Our results confirm that the PUL 1.2 and 2.0 versions detect change in all domains over 2 years. They also demonstrate that simplifying the original scoring of the PUL 1.2 for the revised PUL 2.0 maintains the validity of the construct and enhances the scale measurement qualities. | Notes: | [Mayhew, Anna G.; James, Meredith; Straub, Volker] Newcastle Univ, John Walton Muscular Dystrophy Res Ctr, Inst Genet Med, Newcastle Upon Tyne, Tyne & Wear, England. [Mayhew, Anna G.; James, Meredith; Straub, Volker] Newcastle Hosp NHS Fdn Trust, Cent Pkwy, Newcastle Upon Tyne NE1 3BZ, Tyne & Wear, England. [Coratti, Giorgia; Mazzone, Elena Stacy; Pane, Marika; Mercuri, Eugenio] Univ Cattolica Sacro Cuore, IRCCS Fdn Policlin Gemelli, Child Neurol Unit, Rome, Italy. [Coratti, Giorgia; Mazzone, Elena Stacy; Pane, Marika; Mercuri, Eugenio] Univ Cattolica Sacro Cuore, IRCCS Fdn Policlin Gemelli, Ctr Nemo, Rome, Italy. [Klingels, Katrijn] Univ Leuven, Dept Rehabil Sci, KU Leuven, Heverlee, Belgium. [Klingels, Katrijn] Hasselt Univ, Fac Rehabil Sci, REVAL, Hasselt, Belgium. [Goemans, Natalie] Univ Hosp Leuven, Child Neurol, Leuven, Belgium. | Document URI: | http://hdl.handle.net/1942/29865 | ISSN: | 0012-1622 | e-ISSN: | 1469-8749 | DOI: | 10.1111/dmcn.14361 | ISI #: | 000487491400001 | Rights: | 2019 Mac Keith Press | Category: | A1 | Type: | Journal Contribution | Validations: | ecoom 2020 |
Appears in Collections: | Research publications |
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Develop Med Child Neuro - 2019 - Mayhew - Performance of Upper Limb module for Duchenne muscular dystrophy.pdf | Published version | 782.86 kB | Adobe PDF | View/Open |
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